en Internal Internal case report case report <span style="font-size:14px;"><span style="font-family:times new roman;"><span style="color:#0000FF;"><strong><em>Background: </em></strong></span>Hughes-Stovin Syndrome (HSS) is a rare clinical disorder characterized by deep venous thrombosis and multiple pulmonary and/or bronchial aneurysms. Aneurysms in systemic circulation can also be seen.<br> <span style="color:#0000FF;"><strong>Case presentation:</strong> </span>We report the first case of HSS with aortic aneurysm in a 55-year-old man who initially presented with deep venous thrombosis. The diagnosis of HSS revealing Beh&ccedil;et&rsquo;s disease was made given the history of recurrent oral and genital ulcers. Treatment consisted of 3 daily pulses of methylprednisolone (1g) followed by oral prednisone (1mg/kg daily) and 6 monthly pulses of cyclophosphamide. Oral anticoagulation treatment was&nbsp; held &nbsp;3 months and then was stopped with good outcome.<br> <span style="color:#0000FF;"><strong><em>Conclusion: </em></strong></span>Systemic aneurysms in Hughes Stovin is a worth knowing complication which may reveal Beh&ccedil;et&rsquo;s disease.</span></span> <p></p> Behçet syndrome, Hughes-Stovin syndrome, Aortic aneurysm 332 334 http://caspjim.com/browse.php?a_code=A-10-622-1&slc_lang=en&sid=1 Melek Kechida kechida_mel_lek@hotmail.com 100319475328460010053 100319475328460010053 Yes Department of Internal Medicine and Endocrinology, Fattouma Bourguiba Hospital, University of Monastir, Tunisia Sondes Yaacoubi kechida_mel_lek@hotmail.com 100319475328460010054 100319475328460010054 No Department of Internal Medicine and Endocrinology, Fattouma Bourguiba Hospital, University of Monastir, Tunisia Ahmed Zrig kechida_mel_lek@hotmail.com 100319475328460010055 100319475328460010055 No Department of Radiology, Fattouma Bourguiba Hospital, University of Monastir, Tunisia. Walid Jomaa kechida_mel_lek@hotmailcom 100319475328460010056 100319475328460010056 No Department of Cardiology, Fattouma Bourguiba Hospital, University of Monastir, Tunisia Rim Klii kechida_mel_lek@hotmailcom 100319475328460010057 100319475328460010057 No Department of Internal Medicine and Endocrinology, Fattouma Bourguiba Hospital, University of Monastir, Tunisia Sonia Hammami kechida_mel_lek@hotmailcom 100319475328460010058 100319475328460010058 No Department of Internal Medicine and Endocrinology, Fattouma Bourguiba Hospital, University of Monastir, Tunisia Ines Khochtali kechida_mel_lek@hotmailcom 100319475328460010059 100319475328460010059 No Department of Internal Medicine and Endocrinology, Fattouma Bourguiba Hospital, University of Monastir, Tunisia